Journal of Clinical Pediatrics ›› 2023, Vol. 41 ›› Issue (11): 852-858.doi: 10.12372/jcp.2023.22e0669
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SU Hui, SONG Xiaoxiang, MIN Yue, CHENG Jiang, FENG Qihua(
)
Received:2022-05-11
Published:2023-11-15
Online:2023-11-08
SU Hui, SONG Xiaoxiang, MIN Yue, CHENG Jiang, FENG Qihua. Severe gastrointestinal involvement in juvenile dermatomyositis: a report of three cases[J].Journal of Clinical Pediatrics, 2023, 41(11): 852-858.
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| 病例 序号 | 性别 | 发病 年龄 | 消化道症 状前治疗 | 病程 时间1) | 皮疹 反复2) | 肌力 下降3) | 消化道 症状 | 穿孔部位/ 胰腺炎 | 消化道症 状后治疗 | 手术 治疗 | 穿孔部位 组织病理 | 预后 |
|---|---|---|---|---|---|---|---|---|---|---|---|---|
| 1 | 女 | 4岁4月 | MP冲击→MP+ CTX+IVIG | 9月 | - | + | 腹痛、呕吐、便血 | 胰腺炎 | MP+CsA | - | - | 死亡 |
| 2 | 女 | 8岁 | MP冲击→MP+ CTX+IVIG+血液灌流、血浆置换 | 26月 | - | - | 一过性腹痛 | 穿孔部位不详 | MP+CTX+IVIG | - | - | 好转 |
| 3 | 女 | 2岁7月 | MP冲击→MP+ CTX+IVIG+ 托法替布 | 2月 | - | - | 无 | 穿孔部位不详 | MP+CTX+ 托法替布 | - | - | 好转 |
| 4[ | 女 | 3岁5月 | Pred+MTX | 4月 | - | + | 严重腹痛 | 横结肠穿孔 | MP+MTX+CTX+ 沙利度胺 | + | - | 死亡 |
| 5[ | 女 | 5岁 | Pred+CTX | 12月 | + | + | 腹痛、呕吐 | 十二指肠穿孔 | MP冲击+CTX+IVIG | + | - | 死亡 |
| 6[ | 男 | 3岁3月 | MP+RTX+IVIG | 9月 | + | + | 腹痛、腹胀、腰痛 | 肠穿孔 | MP冲击+CTX+IVIG | - | - | 死亡 |
| 7[ | 女 | 1岁8月 | Pred+CTX+IVIG | 6月 | + | + | 腹痛 | 无 | MP冲击+CTX→ RTX→HSCT | - | - | 完全 缓解 |
| 8[ | 女 | 14.6岁 | Pred+IVIG+AZA | 4月 | + | - | 腹痛、恶心、呕吐 | 结肠穿孔 | Pred+IVIG+AZA | + | 血管异常扩张、血管闭塞,炎症细胞浸润 | 完全 缓解 |
| 9[ | 女 | 13.3岁 | Pred+MTX | 23月 | + | + | 剧烈腹痛 | 十二指肠穿孔 | MP冲击+CsA→ MP+CTX+IVIG | + | 多个中小动脉狭窄或完全闭塞,炎症细胞浸润 | 好转 |
| 10[ | 女 | 6岁 | Pred+CTX | 10月 | - | - | 腹痛 | 右结肠、横结肠穿孔 | Pred | + | - | 完全 缓解 |
| 11[ | 男 | 10岁 | Pred+MTX+AZA | 13月 | - | - | 腹痛 | 十二指肠穿孔 | MP冲击→Pred | + | - | 好转 |
| 12[ | 男 | 14岁 | Pred | 8月 | + | + | 腹痛、呕吐、黄疸 | 胰腺炎 | MP冲击→Pred+CsA | - | - | 好转 |
| 13[ | 男 | 9岁 | Pred | 24月 | - | + | 腹痛、呕吐 | 胰腺炎 | MP冲击+CsA+ IVIG→MP+CTX+ 血浆置换 | - | - | 好转 |
| 14[ | 女 | 7岁 | Pred+MTX+IVIG | 9月 | + | - | 腹痛、呕吐 | 食管、十二指肠穿孔 | MP冲击→Pred+ RTX+CTX+ MTX+IVIG | - | - | 好转 |
| 15[ | 女 | 6岁 | MP冲击→ Pred+MTX | 1月 | + | + | 弥漫性腹痛 | 横结肠穿孔 | Pred+MTX+IVIG+ 更昔洛韦 | + | 结肠黏膜溃疡伴穿孔,内皮细胞中巨细胞病毒包涵体 | 好转 |
| 16[ | 男 | 4岁 | Pred→AZA+ 美洛昔康 | 2月 | - | - | 间歇性腹痛、呕吐 | 十二指肠穿孔 | MP冲击 | + | 黏膜穿孔,邻近黏膜有缺血性改变,炎症细胞浸润 | 好转 |
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